Somatostatinomas are neuroendocrine tumors that produce excessive amounts of somatostatin and are located either in the duodenum or pancreas.
Epidemiology
Incidence – <1/million per year
Age – median age is 40-50 years
Sex – equal gender distribution
Occurrence – sporadic most of the time
Risk Factors
Genetic
Small percentage associated with multiple endocrine neoplasias (MEN 1)
Also may be associated with Von Recklinghausen disease (neurofibromatosis type 1)
Pathophysiology
Locations for tumor – duodenal or pancreatic
Presence of psammoma bodies in the duodenal tumor is suspicious for somatostatinoma
Hormone secretion is somatostatin
Inhibits the release of many hormones (gut hormones including insulin, pancreatic polypeptide, glucagon, gastrin, secretin, glucose-dependent insulinotropic peptide and motilin)
Neurotransmitter function
Significant number of these tumors are metastatic
Clinical Presentation
Somatostatinoma syndrome
Diabetes mellitus – occurs in about 10%
Cholelithiasis
Diarrhea/steatorrhea
Tumor may be found incidentally if not associated with the syndrome (patient will be asymptomatic)
Metastatic disease is frequently found at the time of diagnosis
Diagnosis
Laboratory testing
Somatostatin level – ≥160 pg/mL
Imaging studies
CT and/or MRI
Histological studies
Final confirmation of tumor type – special stains may be required
For fixed tissue samples, consultative services as well as immunohistochemical staining for PGP9.5, somatostatin, synaptophysin and CAM5.2 (LMW) are available
General References
Green BT, Rockey DC.Duodenal somatostatinoma presenting with complete somatostatinoma syndrome.J Clin Gastroenterol. 2001;33(5):415-417. (Link to PubMed)
Hoffmann KM, Furukawa M, Jensen RT.Duodenal neuroendocrine tumors: Classification, functional syndromes, diagnosis and medical treatment.Best Pract Res Clin Gastroenterol. 2005;19(5):675-697. (Link to PubMed)
Kloppel G, Anlauf M.Epidemiology, tumour biology and histopathological classification of neuroendocrine tumours of the gastrointestinal tract.Best Pract Res Clin Gastroenterol. 2005;19(4):507-517. (Link to PubMed)
Stephen AE, Hodin RA.Neuroendocrine tumors of the pancreas, excluding gastrinoma.Surg Oncol Clin N Am. 2006;15(3):497-510. (Link to PubMed)
Tanaka S, Yamasaki S, Matsushita H, Ozawa Y, Kurosaki A, Takeuchi K, Hoshihara Y, Doi T, Watanabe G, Kawaminami K.Duodenal somatostatinoma: a case report and review of 31 cases with special reference to the relationship between tumor size and metastasis.Pathol Int. 2000;50(2):146-152. (Link to PubMed)
Reviewed by
Meikle, A. Wayne, M.D. Medical Director, RIA and Endocrinology at ARUP Laboratories; Professor of Internal Medicine and Pathology, University of Utah
Comprehensive Review: July 2008
Last Update: July 2008