Vasoactive intestinal polypeptide secreting tumor (VIPoma) is a rare endocrine tumor associated with profuse diarrhea.
Epidemiology
Incidence – 1/10 million
Age – median age of onset is 40-50 years
Sex – equal gender distribution
Occurrence – sporadic, although some occur in association with multiple endocrine neoplasia 1 (MEN 1)
Risk Factors
Genetic – around 5% associated with MEN 1 syndrome
Pathophysiology
Epithelial endocrine tumor of endodermal origin of which 50% are malignant
Most tumors have been found in the body and tail of the pancreas and are unifocal
Hormonal secretion is vasoactive intestinal polypeptide (VIP) which is the etiology of the symptoms
VIP is an amino acid polypeptide that binds to intestinal epithelial cells and activates cellular adenylate cyclase and cyclic adenosine monophosphate (cAMP )
Other tumors that can produce VIP include ganglioneuroblastoma, bronchogenic carcinoma, pheochromocytoma, medullary thyroid carcinoma and retroperitoneal histiocytoma
Clinical Presentation
Verner-Morrison syndrome
Watery diarrhea, hypokalemia and achlorhydria (WDHA triad)
Dehydration and renal failure
May occur as a result of profuse diarrhea
Diagnosis
Laboratory testing
VIP level
Elevated >75 pg/mL
Imaging studies
CT/MRI
Histological
Final confirmation of tumor type – special stains may be required
Differential Diagnosis
Gastroenteritis
Other peptide producing tumors – most commonly Zollinger-Ellison (gastrinoma)
For fixed tissue samples, consultative services as well as immunohistochemical staining for CAM5.2 (LMW), PGP9.5 and synaptophysin are available
General References
de Herder WW.Biochemistry of neuroendocrine tumours.Best Pract Res Clin Endocrinol Metab. 2007;21(1):33-41. (Link to PubMed)
Eriksson B, Oberg K, Stridsberg M.Tumor markers in neuroendocrine tumors.Digestion. 2000;62 Suppl 1:33-38. (Link to PubMed)
Peng SY, Li JT, Liu YB, Fang HQ, Wu YL, Peng CH, Wang XB, Qian HR.Diagnosis and treatment of VIPoma in China: (case report and 31 cases review) diagnosis and treatment of VIPoma.Pancreas. 2004;28(1):93-97. (Link to PubMed)
Ram R, Natanzi N, Saadat P, Eliav D, Vadmal MS.Skin metastasis of pancreatic vasoactive intestinal polypeptide tumor: case report and review of the literature.Arch Dermatol. 2006;142(7):946-947. (Link to PubMed)
Smith SL, Branton SA, Avino AJ, Martin JK, Klingler PJ, Thompson GB, Grant CS, van Heerden JA.Vasoactive intestinal polypeptide secreting islet cell tumors: a 15-year experience and review of the literature.Surgery. 1998;124(6):1050-1055. (Link to PubMed)
Stephen AE, Hodin RA.Neuroendocrine tumors of the pancreas, excluding gastrinoma.Surg Oncol Clin N Am. 2006;15(3):497-510. (Link to PubMed)
Reviewed by
Meikle, A. Wayne, M.D. Medical Director, RIA and Endocrinology at ARUP Laboratories; Professor of Internal Medicine and Pathology, University of Utah
Comprehensive Review: July 2008
Last Update: July 2008